Background: This study aims to describe the imaging characteristic of dural sinus malformation in 4 fetuses with different locations. Materials and Methods: We report a series of 4 fetuses with dural sinus malformation in Hubei Maternal and Children's Hospital from July 2013 to February 2016. All the mothers undertook the prenatal magnetic resonance (MRI) imaging because of the intracranial spaceoccupying lesions discovered by prenatal ultrasound. Results: Two of the 4 cases demonstrated typical MRI of dural sinus malformation with thrombosis in the vicinity of torcular herophili (also known as sinus confluence), whereas the other 2 cases showed lesions in the superior sagittal sinus and transverse sinus separately. Three pregnancies were terminated, whereas the other one was delivered in the local hospital. Conclusions: Sonographer should realize the sign of dural sinus malformation. Atypical location of the dural sinus malformation, such as superior sagittal sinus and transverse sinus, should be paid special attention to. Further, prenatal MRI is necessary to identify the lesion.